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@ARTICLE{Joshi:138036,
author = {Joshi, Yashashree and Sória, Marília Grando and Quadrato,
Giorgia and Inak, Gizem and Zhou, Luming and Hervera, Arnau
and Rathore, Khizr I and Elnaggar, Mohamed and Cucchiarini,
Magali and Magali, Cucchiarini and Marine, Jeanne Christophe
and Puttagunta, Radhika and Di Giovanni, Simone},
title = {{T}he {MDM}4/{MDM}2-p53-{IGF}1 axis controls axonal
regeneration, sprouting and functional recovery after {CNS}
injury.},
journal = {Brain},
volume = {138},
number = {7},
issn = {0006-8950},
address = {Oxford},
publisher = {Oxford Univ. Press},
reportid = {DZNE-2020-04358},
pages = {1843-1862},
year = {2015},
abstract = {Regeneration of injured central nervous system axons is
highly restricted, causing neurological impairment. To date,
although the lack of intrinsic regenerative potential is
well described, a key regulatory molecular mechanism for the
enhancement of both axonal regrowth and functional recovery
after central nervous system injury remains elusive. While
ubiquitin ligases coordinate neuronal morphogenesis and
connectivity during development as well as after axonal
injury, their role specifically in axonal regeneration is
unknown. Following a bioinformatics network analysis
combining ubiquitin ligases with previously defined axonal
regenerative proteins, we found a triad composed of the
ubiquitin ligases MDM4, MDM2 and the transcription factor
p53 (encoded by TP53) as a putative central signalling
complex restricting the regeneration program. Indeed,
conditional deletion of MDM4 or pharmacological inhibition
of MDM2/p53 interaction in the eye and spinal cord promote
axonal regeneration and sprouting of the optic nerve after
crush and of supraspinal tracts after spinal cord injury.
The double conditional deletion of MDM4-p53 as well as MDM2
inhibition in p53-deficient mice blocks this regenerative
phenotype, showing its dependence upon p53. Genome-wide gene
expression analysis from ex vivo fluorescence-activated cell
sorting in MDM4-deficient retinal ganglion cells identifies
the downstream target IGF1R, whose activity and expression
was found to be required for the regeneration elicited by
MDM4 deletion. Importantly, we demonstrate that
pharmacological enhancement of the MDM2/p53-IGF1R axis
enhances axonal sprouting as well as functional recovery
after spinal cord injury. Thus, our results show
MDM4-MDM2/p53-IGF1R as an original regulatory mechanism for
CNS regeneration and offer novel targets to enhance
neurological
$recovery.media-1vid110.1093/brain/awv125_video_abstractawv125_video_abstract.$},
keywords = {Animals / Axons: metabolism / Axons: pathology /
Computational Biology / Disease Models, Animal / Flow
Cytometry / Immunoblotting / Immunohistochemistry /
Immunoprecipitation / Insulin-Like Growth Factor I:
metabolism / Mice / Mice, Inbred C57BL / Mice, Mutant
Strains / Nerve Crush / Nerve Regeneration: physiology /
Optic Nerve Injuries: metabolism / Optic Nerve Injuries:
pathology / Optic Nerve Injuries: physiopathology /
Proto-Oncogene Proteins: metabolism / Proto-Oncogene
Proteins c-mdm2: metabolism / Recovery of Function:
physiology / Reverse Transcriptase Polymerase Chain Reaction
/ Signal Transduction: physiology / Spinal Cord Injuries:
metabolism / Spinal Cord Injuries: pathology / Spinal Cord
Injuries: physiopathology / Transcriptome / Tumor Suppressor
Protein p53: metabolism / Ubiquitin-Protein Ligases:
metabolism / Mdm4 protein, mouse (NLM Chemicals) /
Proto-Oncogene Proteins (NLM Chemicals) / Tumor Suppressor
Protein p53 (NLM Chemicals) / insulin-like growth factor-1,
mouse (NLM Chemicals) / Insulin-Like Growth Factor I (NLM
Chemicals) / Mdm2 protein, mouse (NLM Chemicals) /
Proto-Oncogene Proteins c-mdm2 (NLM Chemicals) /
Ubiquitin-Protein Ligases (NLM Chemicals)},
cin = {AG N.N. 3},
ddc = {610},
cid = {I:(DE-2719)1240015},
pnm = {344 - Clinical and Health Care Research (POF3-344)},
pid = {G:(DE-HGF)POF3-344},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:25981963},
doi = {10.1093/brain/awv125},
url = {https://pub.dzne.de/record/138036},
}