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@ARTICLE{Rattay:141598,
author = {Rattay, Tim W and Boldt, Andreas and Völker, Maximilian
and Wiethoff, Sarah and Hengel, Holger and Schüle, Rebecca
and Schöls, Ludger},
title = {{N}on-motor symptoms are relevant and possibly treatable in
hereditary spastic paraplegia type 4 ({SPG}4).},
journal = {Journal of neurology},
volume = {267},
number = {2},
issn = {0340-5354},
address = {Berlin},
publisher = {Springer77118},
reportid = {DZNE-2020-07922},
pages = {369-379},
year = {2020},
abstract = {Hereditary spastic paraplegias (HSP) share as cardinal
feature progressive spastic gait disorder. SPG4 accounts for
about $25\%$ of cases and is caused by mutations in the
SPAST gene. Although HSP is an upper motor neuron disease,
the relevance of non-motor symptoms is increasingly
recognized because of the potential response to treatment.
Our study sets out to evaluate non-motor symptoms and their
relevance with regard to health-related quality of life. In
118 genetically confirmed SPG4 cases and age- and
gender-matched controls, validated questionnaires were used
to evaluate fatigue, depression, pain, and restless legs
syndrome. In addition, self-reported medical information was
collected concerning comorbidities and bladder, bowel, and
sexual dysfunction. In a sub-study, cognition was evaluated
using the CANTAB® test-battery and the Montreal Cognitive
Assessment in 26 SPG4 patients. We found depression and pain
to be significantly increased. The frequency of restless
legs syndrome varied largely depending on defining criteria.
There were no significant deficits in cognition as examined
by CANTAB® despite a significant increase in self-reported
memory impairment in SPG4 patients. Bladder, sexual, and
defecation problems were frequent and seemed to be
underrecognized in current treatment strategies. All
identified non-motor symptoms correlated with health-related
quality of life, which was reduced in SPG4 compared to
controls. We recommend that clinicians regularly screen for
depression, pain, and fatigue and ask for bladder, sexual,
and defecation problems to recognize and treat non-motor
symptoms accordingly to improve quality of life in patients
with SPG4.},
keywords = {Adult / Aged / Cognition Disorders: etiology / Cognition
Disorders: psychology / Depression: etiology / Depression:
psychology / Fatigue: etiology / Fatigue: psychology / Fecal
Incontinence: etiology / Female / Humans / Male / Memory
Disorders: etiology / Mental Status and Dementia Tests /
Middle Aged / Pain: etiology / Paraplegia: physiopathology /
Paraplegia: psychology / Paraplegia: therapy / Quality of
Life / Restless Legs Syndrome: etiology / Restless Legs
Syndrome: psychology / Self Report / Sexual Dysfunction,
Physiological: etiology / Spastic Paraplegia, Hereditary:
physiopathology / Spastic Paraplegia, Hereditary: psychology
/ Spastic Paraplegia, Hereditary: therapy / Urinary Bladder
Diseases: etiology / Young Adult},
cin = {AG Gasser / AG Maetzler / AG Schöls},
ddc = {610},
cid = {I:(DE-2719)1210000 / I:(DE-2719)5000024 /
I:(DE-2719)5000005},
pnm = {345 - Population Studies and Genetics (POF3-345) / 344 -
Clinical and Health Care Research (POF3-344)},
pid = {G:(DE-HGF)POF3-345 / G:(DE-HGF)POF3-344},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:31646384},
doi = {10.1007/s00415-019-09573-w},
url = {https://pub.dzne.de/record/141598},
}