TY - JOUR
AU - Traschuetz, Andreas
AU - Cortese, Andrea
AU - Reich, Selina
AU - Dominik, Natalia
AU - Faber, Jennifer
AU - Jacobi, Heike
AU - Hartmann, Annette M
AU - Rujescu, Dan
AU - Montaut, Solveig
AU - Echaniz-Laguna, Andoni
AU - Erer, Sevda
AU - Schütz, Valerie Cornelia
AU - Tarnutzer, Alexander A
AU - Sturm, Marc
AU - Haack, Tobias B
AU - Vaucamps-Diedhiou, Nadège
AU - Puccio, Helene
AU - Schöls, Ludger
AU - Klockgether, Thomas
AU - van de Warrenburg, Bart P
AU - Paucar, Martin
AU - Timmann, Dagmar
AU - Hilgers, Ralf-Dieter
AU - Gazulla, Jose
AU - Strupp, Michael
AU - Moris, German
AU - Filla, Alessandro
AU - Houlden, Henry
AU - Anheim, Mathieu
AU - Infante, Jon
AU - Basak, A Nazli
AU - Synofzik, Matthis
AU - Barut, Banu Özen
AU - Bilgic, Basar
AU - Boz, Cavit
AU - Cauquil, Cécile
AU - Deininger, Natalie
AU - Dufke, Claudia
AU - Elibol, Bülent
AU - Erbas, Furkan
AU - Ertan, Sibel
AU - Genc, Fatma
AU - Giegling, Ina
AU - Parman, Yesim
AU - Rossi, Salvatore
AU - Salcin, Celal
AU - Tan, Meliha
AU - Taştekin, Hilal
AU - Tranchant, Christine
AU - Uygun, Günes
AU - Yassa, Özge Yagcioglu
TI - Natural History, Phenotypic Spectrum, and Discriminative Features of Multisystemic RFC1 Disease.
JO - Neurology
VL - 96
IS - 9
SN - 1526-632X
CY - [S.l.]
PB - Ovid
M1 - DZNE-2021-01155
SP - e1369 - e1382
PY - 2021
AB - To delineate the full phenotypic spectrum, discriminative features, piloting longitudinal progression data, and sample size calculations of replication factor complex subunit 1 (RFC1) repeat expansions, recently identified as causing cerebellar ataxia, neuropathy, vestibular areflexia syndrome (CANVAS).Multimodal RFC1 repeat screening (PCR, Southern blot, whole-exome/genome sequencing-based approaches) combined with cross-sectional and longitudinal deep phenotyping in (1) cross-European cohort A (70 families) with ≥2 features of CANVAS or ataxia with chronic cough (ACC) and (2) Turkish cohort B (105 families) with unselected late-onset ataxia.Prevalence of RFC1 disease was 67
KW - Adult
KW - Aged
KW - Ataxia
KW - Bilateral Vestibulopathy
KW - Cohort Studies
KW - DNA Repeat Expansion
KW - Disease Progression
KW - Europe
KW - Exome
KW - Female
KW - Genetic Testing
KW - Humans
KW - Magnetic Resonance Imaging
KW - Male
KW - Middle Aged
KW - Multiple System Atrophy: diagnosis
KW - Multiple System Atrophy: diagnostic imaging
KW - Multiple System Atrophy: genetics
KW - Phenotype
KW - Predictive Value of Tests
KW - Replication Protein C: genetics
KW - Turkey
KW - Vestibular Diseases
KW - RFC1 protein, human (NLM Chemicals)
KW - Replication Protein C (NLM Chemicals)
LB - PUB:(DE-HGF)16
C6 - pmid:33495376
C2 - pmc:PMC8055326
DO - DOI:10.1212/WNL.0000000000011528
UR - https://pub.dzne.de/record/156023
ER -