000157830 001__ 157830 000157830 005__ 20230915094042.0 000157830 0247_ $$2doi$$a10.1016/bs.pmbts.2020.03.009 000157830 0247_ $$2doi$$a10.1016/bs.pmbts.2020.03.009 000157830 0247_ $$2pmid$$apmid:32620242 000157830 0247_ $$2ISSN$$a0079-6603 000157830 0247_ $$2ISSN$$a1877-1173 000157830 0247_ $$2ISSN$$a1878-0814 000157830 0247_ $$2ISSN$$a2211-9108 000157830 037__ $$aDZNE-2021-01287 000157830 082__ $$a530 000157830 1001_ $$0P:(DE-2719)9000726$$aRodriguez-Muela, Natalia$$b0$$eFirst author$$udzne 000157830 245__ $$aAutophagy in motor neuron diseases 000157830 260__ $$aAmsterdam [u.a.]$$bElsevier$$c2020 000157830 3367_ $$2DRIVER$$aarticle 000157830 3367_ $$2DataCite$$aOutput Types/Journal article 000157830 3367_ $$0PUB:(DE-HGF)16$$2PUB:(DE-HGF)$$aJournal Article$$bjournal$$mjournal$$s1632320839_31140$$xReview Article 000157830 3367_ $$2BibTeX$$aARTICLE 000157830 3367_ $$2ORCID$$aJOURNAL_ARTICLE 000157830 3367_ $$00$$2EndNote$$aJournal Article 000157830 520__ $$aMotor neuron diseases (MNDs) are a wide group of neurodegenerative disorders characterized by the degeneration of a specific neuronal type located in the central nervous system, the motor neuron (MN). There are two main types of MNs, spinal and cortical MNs and depending on the type of MND, one or both types are affected. Cortical MNs innervate spinal MNs and these control a variety of cellular targets, being skeletal muscle their main one which is also affected in MNDs. A correct functionality of autophagy is necessary for the survival of all cellular types and it is particularly crucial for neurons, given their postmitotic and highly specialized nature. Numerous studies have identified alterations of autophagy activity in multiple MNDs. The scientific community has been particularly prolific in reporting the role that autophagy plays in the most common adult MND, amyotrophic lateral sclerosis, although many studies have started to identify physiological and pathological functions of this catabolic system in other MNDs, such as spinal muscular atrophy and spinal and bulbar muscular atrophy. The degradation of selective cargo by autophagy and how this process is altered upon the presence of MND-causing mutations is currently also a matter of intense investigation, particularly regarding the selective autophagic clearance of mitochondria. Thorough reviews on this field have been recently published. This chapter will cover the current knowledge on the functionality of autophagy and lysosomal homeostasis in the main MNDs and other autophagy-related topics in the MND field that have risen special interest in the research community. 000157830 536__ $$0G:(DE-HGF)POF4-352$$a352 - Disease Mechanisms (POF4-352)$$cPOF4-352$$fPOF IV$$x0 000157830 650_2 $$2MeSH$$aAdult 000157830 650_2 $$2MeSH$$aAmyotrophic Lateral Sclerosis: genetics 000157830 650_2 $$2MeSH$$aAmyotrophic Lateral Sclerosis: pathology 000157830 650_2 $$2MeSH$$aAnimals 000157830 650_2 $$2MeSH$$aAutophagy: drug effects 000157830 650_2 $$2MeSH$$aAutophagy: physiology 000157830 650_2 $$2MeSH$$aAutophagy-Related Proteins: genetics 000157830 650_2 $$2MeSH$$aAutophagy-Related Proteins: physiology 000157830 650_2 $$2MeSH$$aC9orf72 Protein: deficiency 000157830 650_2 $$2MeSH$$aC9orf72 Protein: genetics 000157830 650_2 $$2MeSH$$aC9orf72 Protein: physiology 000157830 650_2 $$2MeSH$$aDNA Repeat Expansion 000157830 650_2 $$2MeSH$$aDisease Models, Animal 000157830 650_2 $$2MeSH$$aEndocytosis 000157830 650_2 $$2MeSH$$aHumans 000157830 650_2 $$2MeSH$$aMice, Transgenic 000157830 650_2 $$2MeSH$$aMotor Neuron Disease: genetics 000157830 650_2 $$2MeSH$$aMotor Neuron Disease: pathology 000157830 650_2 $$2MeSH$$aMuscular Atrophy, Spinal: genetics 000157830 650_2 $$2MeSH$$aMuscular Atrophy, Spinal: pathology 000157830 650_2 $$2MeSH$$aMutation 000157830 650_2 $$2MeSH$$aNeurodegenerative Diseases: genetics 000157830 650_2 $$2MeSH$$aNeurodegenerative Diseases: pathology 000157830 650_2 $$2MeSH$$aOrganelles 000157830 650_2 $$2MeSH$$aRNA-Binding Protein FUS: deficiency 000157830 650_2 $$2MeSH$$aRNA-Binding Protein FUS: genetics 000157830 650_2 $$2MeSH$$aRNA-Binding Protein FUS: physiology 000157830 650_2 $$2MeSH$$aTDP-43 Proteinopathies: genetics 000157830 650_2 $$2MeSH$$aTDP-43 Proteinopathies: pathology 000157830 773__ $$0PERI:(DE-600)2474898-5$$a10.1016/bs.pmbts.2020.03.009 $$p157-202$$tProgress in molecular biology and translational science$$v172$$x1877-1173$$y2020 000157830 909CO $$ooai:pub.dzne.de:157830$$pVDB 000157830 9101_ $$0I:(DE-588)1065079516$$6P:(DE-2719)9000726$$aDeutsches Zentrum für Neurodegenerative Erkrankungen$$b0$$kDZNE 000157830 9131_ $$0G:(DE-HGF)POF4-352$$1G:(DE-HGF)POF4-350$$2G:(DE-HGF)POF4-300$$3G:(DE-HGF)POF4$$4G:(DE-HGF)POF$$aDE-HGF$$bGesundheit$$lNeurodegenerative Diseases$$vDisease Mechanisms$$x0 000157830 9141_ $$y2020 000157830 915__ $$0StatID:(DE-HGF)0160$$2StatID$$aDBCoverage$$bEssential Science Indicators$$d2021-02-02 000157830 915__ $$0StatID:(DE-HGF)0113$$2StatID$$aWoS$$bScience Citation Index Expanded$$d2021-02-02 000157830 915__ $$0StatID:(DE-HGF)0100$$2StatID$$aJCR$$bPROG MOL BIOL TRANSL : 2021$$d2023-03-30 000157830 915__ $$0StatID:(DE-HGF)0200$$2StatID$$aDBCoverage$$bSCOPUS$$d2023-03-30 000157830 915__ $$0StatID:(DE-HGF)0300$$2StatID$$aDBCoverage$$bMedline$$d2023-03-30 000157830 915__ $$0StatID:(DE-HGF)9900$$2StatID$$aIF < 5$$d2023-03-30 000157830 9201_ $$0I:(DE-2719)1713001$$kAG Rodriguez-Muela$$lSelective Neuronal Vulnerability in Neurodegenerative Diseases$$x0 000157830 980__ $$ajournal 000157830 980__ $$aVDB 000157830 980__ $$aI:(DE-2719)1713001 000157830 980__ $$aUNRESTRICTED