% IMPORTANT: The following is UTF-8 encoded. This means that in the presence
% of non-ASCII characters, it will not work with BibTeX 0.99 or older.
% Instead, you should use an up-to-date BibTeX implementation like “bibtex8” or
% “biber”.
@ARTICLE{Klopstock:163395,
author = {Klopstock, Thomas and Priglinger, Claudia and Yilmaz, Ali
and Kornblum, Cornelia and Distelmaier, Felix and Prokisch,
Holger},
title = {{M}itochondrial {D}isorders.},
journal = {Deutsches Ärzteblatt international},
volume = {118},
number = {44},
issn = {1866-0452},
address = {Köln},
publisher = {Dt. Ärzte-Verl.},
reportid = {DZNE-2022-00157},
pages = {741-748},
year = {2021},
abstract = {Mitochondrial disorders are among the most common heritable
diseases, with an overall lifetime risk of approximately one
in 1500. Nonetheless, their diagnosis is often missed
because of their extreme phenotypic and genotypic
heterogeneity.This review is based on publications retrieved
by a selective literature search on the clinical features,
genetics, pathogenesis, diagnosis, and treatment of
mitochondrial diseases.Pathogenic defects of energy
metabolism have been described to date in over 400 genes.
Only a small number of these genes lie in the mitochondrial
DNA; the corresponding diseases are either maternally
inherited or of sporadic distribution. The remaining
disease-associated genes are coded in nuclear DNA and cause
diseases that are inherited according to Mendelian rules,
mostly autosomal recessive. The most severely involved
organs are generally those with the highest energy
requirements, including the brain, the sensory epithelia,
and the extraocular, cardiac, and skeletal musculature.
Typical manifestations include epileptic seizures,
stroke-like episodes, hearing loss, retinopathy, external
ophthalmoparesis, exercise intolerance, and diabetes
mellitus. More than two manifestations of these types should
arouse suspicion of a disease of energy metabolism. The
severity of mitochondrial disorders ranges from very severe
disease, already evident in childhood, to relatively mild
disease arising in late adulthood. The diagnosis is usually
confirmed with molecular-genetic methods. Symptomatic
treatment can improve patients' quality of life. The only
disease-modifying treatment that has been approved to date
is idebenone for the treatment of Leber hereditary optic
neuropathy. Intravitreal gene therapy has also been
developed for the treatment of this disease; its approval by
the European Medicines Agency is pending.Patients with
mitochondrial diseases have highly varied manifestations and
can thus present to physicians in practically any branch of
medicine. A correct diagnosis is the prerequisite for
genetic counseling and for the initiation of personalized
treatment.},
subtyp = {Review Article},
keywords = {Adult / DNA, Mitochondrial: genetics / Humans /
Mitochondrial Diseases: diagnosis / Mitochondrial Diseases:
genetics / Mitochondrial Diseases: therapy / Optic Atrophy,
Hereditary, Leber / Quality of Life / DNA, Mitochondrial
(NLM Chemicals)},
cin = {Clinical Research (Munich)},
ddc = {610},
cid = {I:(DE-2719)1111015},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:34158150},
pmc = {pmc:PMC8830351},
doi = {10.3238/arztebl.m2021.0251},
url = {https://pub.dzne.de/record/163395},
}