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@ARTICLE{Liu:164533,
author = {Liu, Hui and Dehestani, Mohammad and Blauwendraat, Cornelis
and Makarious, Mary B and Leonard, Hampton L and Kim,
Jonggeol J and Schulte, Claudia and Noyce, Alastair and
Jacobs, Benjamin M and Foote, Isabelle and Sharma, Manu and
Genetics, Comprehensive Unbiased Risk factor Assessment for
and Nalls, Mike and Singleton, Andrew and Gasser, Thomas and
Bandres-Ciga, Sara},
collaboration = {Consortium, International Parkinson's Disease Genomics and
Disease, Environment in Parkinson's},
title = {{P}olygenic resilience modulates the penetrance of
{P}arkinson's disease genetic risk factors.},
journal = {Annals of neurology},
volume = {92},
number = {2},
issn = {0364-5134},
address = {Hoboken, NJ},
publisher = {Wiley-Blackwell},
reportid = {DZNE-2022-01082},
pages = {270-278},
year = {2022},
note = {CC BY-NC-ND},
abstract = {The aim of the current study is to understand why some
individuals avoid developing Parkinson's disease (PD) in
spite of being at relatively high genetic risk, using the
largest datasets of individual-level genetic data
available.We calculated polygenic risk score to identify
controls and matched PD cases with the highest burden of
genetic risk for PD in the discovery cohort (IPDGC, 7,204 PD
cases and 9,412 controls) and validation cohorts
(COURAGE-PD, 8,968 cases and 7,598 controls; UKBB, 2,639 PD
cases and 14,301 controls; AMP-PD, 2,248 cases and 2,817
controls). A genome-wide association study meta-analysis was
performed on these individuals to understand genetic
variation associated with resistance to disease. We further
constructed a polygenic resilience score, performed MAGMA
gene-based analyses and functional enrichment analyses.A
higher polygenic resilience score was associated with a
lower risk for PD (Beta= -0.054, SE = 0.022; P = 0.013).
Although no single locus reached genome-wide significance,
MAGMA gene-based analyses nominated TBCA as a putative gene.
Furthermore, we estimated the narrow-sense heritability
associated with resilience to PD (h2 = 0.081, SE = 0.035, P
= 0.0003). Subsequent functional enrichment analysis
highlighted histone methylation as potential pathway
harboring resilience alleles that could mitigate the effects
of PD risk loci.The present study represents a novel and
comprehensive assessment of heritable genetic variation
contributing to PD resistance. We show that a genetic
resilience score can modify the penetrance of PD genetic
risk factors and therefore protect individuals carrying a
high-risk genetic burden from developing PD. This article is
protected by copyright. All rights reserved.},
keywords = {Parkinson's disease (Other) / genetics (Other) / polygenic
risk (Other) / resilience (Other)},
cin = {AG Gasser / Tübingen common / Ext HIH},
ddc = {610},
cid = {I:(DE-2719)1210000 / I:(DE-2719)6000018 /
I:(DE-2719)5000057},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:35599344},
doi = {10.1002/ana.26416},
url = {https://pub.dzne.de/record/164533},
}