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@ARTICLE{Ali:164570,
author = {Ali, Muhammad and Sung, Yun Ju and Wang, Fengxian and
Fernández, Maria V and Morris, John C and Fagan, Anne M and
Blennow, Kaj and Zetterberg, Henrik and Heslegrave, Amanda
and Johansson, Per M and Svensson, Johan and Nellgård,
Bengt and Lleó, Alberto and Alcolea, Daniel and Clarimon,
Jordi and Rami, Lorena and Molinuevo, José Luis and
Suárez-Calvet, Marc and Morenas Rodriguez, Estrella and
Kleinberger, Gernot and Haass, Christian and Ewers, Michael
and Levin, Johannes and Farlow, Martin R and Perrin, Richard
J and Cruchaga, Carlos},
collaboration = {Initiative, Alzheimer’s Disease Neuroimaging and Network,
Dominantly Inherited Alzheimer},
title = {{L}everaging large multi-center cohorts of {A}lzheimer
disease endophenotypes to understand the role of {K}lotho
heterozygosity on disease risk.},
journal = {PLOS ONE},
volume = {17},
number = {5},
issn = {1932-6203},
address = {San Francisco, California, US},
publisher = {PLOS},
reportid = {DZNE-2022-01119},
pages = {e0267298},
year = {2022},
abstract = {Two genetic variants in strong linkage disequilibrium
(rs9536314 and rs9527025) in the Klotho (KL) gene, encoding
a transmembrane protein, implicated in longevity and
associated with brain resilience during normal aging, were
recently shown to be associated with Alzheimer disease (AD)
risk in cognitively normal participants who are APOE ε4
carriers. Specifically, the participants heterozygous for
this variant (KL-SVHET+) showed lower risk of developing AD.
Furthermore, a neuroprotective effect of KL-VSHET+ has been
suggested against amyloid burden for cognitively normal
participants, potentially mediated via the regulation of
redox pathways. However, inconsistent associations and a
smaller sample size of existing studies pose significant
hurdles in drawing definitive conclusions. Here, we
performed a well-powered association analysis between
KL-VSHET+ and five different AD endophenotypes; brain
amyloidosis measured by positron emission tomography (PET)
scans (n = 5,541) or cerebrospinal fluid Aβ42 levels (CSF;
n = 5,093), as well as biomarkers associated with tau
pathology: the CSF Tau (n = 5,127), phosphorylated Tau
(pTau181; n = 4,778) and inflammation: CSF soluble
triggering receptor expressed on myeloid cells 2 (sTREM2; n
= 2,123) levels. Our results found nominally significant
associations of KL-VSHET+ status with biomarkers for brain
amyloidosis (e.g., CSF Aβ positivity; odds ratio [OR] =
0.67 $[95\%$ CI, 0.55-0.78], β = 0.72, p = 0.007) and tau
pathology (e.g., biomarker positivity for CSF Tau; OR = 0.39
$[95\%$ CI, 0.19-0.77], β = -0.94, p = 0.007, and pTau; OR
= 0.50 $[95\%$ CI, 0.27-0.96], β = -0.68, p = 0.04) in
cognitively normal participants, 60-80 years old, who are
APOE e4-carriers. Our work supports previous findings,
suggesting that the KL-VSHET+ on an APOE ε4 genotype
background may modulate Aβ and tau pathology, thereby
lowering the intensity of neurodegeneration and incidence of
cognitive decline in older controls susceptible to AD.},
keywords = {Aged / Aged, 80 and over / Alzheimer Disease: cerebrospinal
fluid / Alzheimer Disease: genetics / Amyloid beta-Peptides:
metabolism / Amyloidosis / Apolipoprotein E4: genetics /
Biomarkers: cerebrospinal fluid / Disease Susceptibility /
Endophenotypes / Humans / Middle Aged / Peptide Fragments:
genetics / Positron-Emission Tomography / tau Proteins:
cerebrospinal fluid / tau Proteins: genetics / Amyloid
beta-Peptides (NLM Chemicals) / Apolipoprotein E4 (NLM
Chemicals) / Biomarkers (NLM Chemicals) / Peptide Fragments
(NLM Chemicals) / tau Proteins (NLM Chemicals)},
cin = {AG Haass / AG Levin},
ddc = {610},
cid = {I:(DE-2719)1110007 / I:(DE-2719)1111016},
pnm = {352 - Disease Mechanisms (POF4-352) / 353 - Clinical and
Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-352 / G:(DE-HGF)POF4-353},
experiment = {EXP:(DE-2719)DIAN-20090101},
typ = {PUB:(DE-HGF)16},
pmc = {pmc:PMC9135221},
pubmed = {pmid:35617280},
doi = {10.1371/journal.pone.0267298},
url = {https://pub.dzne.de/record/164570},
}