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@ARTICLE{Eninger:164654,
author = {Eninger, Timo and Müller, Stephan A. and Bacioglu, Mehtap
and Schweighauser, Manuel and Lambert, Marius and Maia, Luis
F. and Neher, Jonas and Hornfeck, Sarah M and Obermüller,
Ulrike and Kleinberger, Gernot and Haass, Christian and
Kahle, Philipp and Staufenbiel, Matthias and Ping, Lingyan
and Duong, Duc M. and Levey, Allan I. and Seyfried, Nicholas
T. and Lichtenthaler, Stefan and Jucker, Mathias and Kaeser,
Stephan A.},
title = {{S}ignatures of glial activity can be detected in the {CSF}
proteome},
journal = {Proceedings of the National Academy of Sciences of the
United States of America},
volume = {119},
number = {24},
issn = {0027-8424},
address = {Washington, DC},
publisher = {National Acad. of Sciences},
reportid = {DZNE-2022-01184},
pages = {e2119804119},
year = {2022},
abstract = {Single-cell transcriptomics has revealed specific glial
activation states associated with the pathogenesis of
neurodegenerative diseases, such as Alzheimer’s and
Parkinson’s disease. While these findings may eventually
lead to new therapeutic opportunities, little is known about
how these glial responses are reflected by biomarker changes
in bodily fluids. Such knowledge, however, appears crucial
for patient stratification, as well as monitoring disease
progression and treatment responses in clinical trials.
Here, we took advantage of well-described mouse models of
β-amyloidosis and α-synucleinopathy to explore
cerebrospinal fluid (CSF) proteome changes related to their
respective proteopathic lesions. Nontargeted liquid
chromatography-mass spectrometry revealed that the majority
of proteins that undergo age-related changes in CSF of
either mouse model were linked to microglia and astrocytes.
Specifically, we identified a panel of more than 20
glial-derived proteins that were increased in CSF of aged
β-amyloid precursor protein- and α-synuclein-transgenic
mice and largely overlap with previously described
disease-associated glial genes identified by single-cell
transcriptomics. Our results also show that enhanced
shedding is responsible for the increase of several of the
identified glial CSF proteins as exemplified for TREM2.
Notably, the vast majority of these proteins can also be
quantified in human CSF and reveal changes in Alzheimer’s
disease cohorts. The finding that cellular transcriptome
changes translate into corresponding changes of CSF proteins
is of clinical relevance, supporting efforts to identify
fluid biomarkers that reflect the various functional states
of glial responses in cerebral proteopathies, such as
Alzheimer’s and Parkinson’s disease.},
keywords = {Alzheimer Disease: cerebrospinal fluid / Alzheimer Disease:
metabolism / Animals / Biomarkers: cerebrospinal fluid /
Cerebrospinal Fluid: metabolism / Gene Expression Profiling
/ Humans / Mice / Neuroglia: metabolism / Parkinson Disease:
cerebrospinal fluid / Parkinson Disease: metabolism /
Proteome: metabolism / Single-Cell Analysis / tau Proteins},
cin = {AG Jucker / AG Lichtenthaler / AG Neher / AG Herms / AG
Haass / AG Kahle / Ext UKT},
ddc = {500},
cid = {I:(DE-2719)1210001 / I:(DE-2719)1110006 /
I:(DE-2719)1210012 / I:(DE-2719)1110001 / I:(DE-2719)1110007
/ I:(DE-2719)1210000-4 / I:(DE-2719)5000058},
pnm = {352 - Disease Mechanisms (POF4-352)},
pid = {G:(DE-HGF)POF4-352},
typ = {PUB:(DE-HGF)16},
pmc = {pmc:PMC9214531},
pubmed = {pmid:35666874},
doi = {10.1073/pnas.2119804119},
url = {https://pub.dzne.de/record/164654},
}