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@ARTICLE{JecmenicaLukic:164981,
author = {Jecmenica Lukic, Milica and Respondek, Gesine and Kurz,
Carolin and Compta, Yaroslau and Gelpi, Ellen and Ferguson,
Leslie W and Rajput, Alex and Troakes, Claire and van
Swieten, John C and Giese, Armin and Roeber, Sigrun and
Herms, Jochen and Arzberger, Thomas and Höglinger, Günter
and Giese, Armin and Troakes, Claire and Gelpi, Ellen and
Respondek, Gesine and Höglinger, Günter U and van Swieten,
John and Arzberger, Thomas and Compta, Yaroslau and
Molina-Porcel, L. and Aldecoa, I. and Tolosa, E. and Martí,
M. J. and Valldeoriola, F. and Pagonabarraga, J. and Calopa,
M. and Bayès, A. and Hernandez, I. and Aguilar, M. and
Genis, D.},
collaboration = {group, MDS-endorsed PSP study},
title = {{L}ong-duration progressive supranuclear palsy: clinical
course and pathological underpinnings.},
journal = {Annals of neurology},
volume = {92},
number = {4},
issn = {0364-5134},
address = {Hoboken, NJ},
publisher = {Wiley-Blackwell},
reportid = {DZNE-2022-01385},
pages = {637-649},
year = {2022},
abstract = {To identify the clinical characteristics of the subgroup of
benign progressive supranuclear palsy with particularly long
disease duration; to define neuropathological determinants
underlying variability in disease duration in progressive
supranuclear palsy.Clinical and pathological features were
compared among 186 autopsy-confirmed cases with progressive
supranuclear palsy with ≥10 years and shorter survival
times.45 cases $(24.2\%)$ had a disease duration of ≥10
years. The absence of ocular motor abnormalities within the
first 3 years from disease onset was the only significant
independent clinical predictor of longer survival.
Histopathologically, the neurodegeneration parameters in
each survival group were paralleled anatomically by the
distribution of neuronal cytoplasmic inclusions, whereas the
tufted astrocytes displayed anatomically an opposite
severity pattern. Most interestingly, we found significantly
less coiled bodies in those who survive longer, in contrast
to patients with less favorable course.A considerable
proportion of patients had a more 'benign' disease course
with ≥10 years survival. They had a distinct pattern and
evolution of core symptoms compared to patients with short
survival. The inverted anatomical patterns of astrocytic tau
distribution suggest distinct implications of these cell
types in trans-cellular propagation. The tempo of disease
progression appeared to be determined mostly by
oligodendroglial tau, where high degree of oligodendroglial
tau pathology might affect neuronal integrity and function
on top of neuronal tau pathology. The relative contribution
of glial tau should be further explored in cellular and
animal models. This article is protected by copyright. All
rights reserved.},
keywords = {Astrocytes: metabolism / Autopsy / Disease Progression /
Humans / Neurons: metabolism / Supranuclear Palsy,
Progressive: pathology / tau Proteins: metabolism},
cin = {AG Höglinger 2 / Neuropathology / Brainbank / AG Herms},
ddc = {610},
cid = {I:(DE-2719)1111015 / I:(DE-2719)1140013 /
I:(DE-2719)1110001},
pnm = {353 - Clinical and Health Care Research (POF4-353) / 352 -
Disease Mechanisms (POF4-352)},
pid = {G:(DE-HGF)POF4-353 / G:(DE-HGF)POF4-352},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:35872640},
doi = {10.1002/ana.26455},
url = {https://pub.dzne.de/record/164981},
}