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@ARTICLE{Distelmaier:255493,
author = {Distelmaier, Felix and Klopstock, Thomas},
title = {{N}euroimaging in mitochondrial disease.},
journal = {Handbook of clinical neurology},
volume = {194},
issn = {0072-9752},
address = {Amsterdam [u.a.]},
publisher = {Elsevier},
reportid = {DZNE-2023-00294},
pages = {173-185},
year = {2023},
abstract = {The anatomic complexity of the brain in combination with
its high energy demands makes this organ specifically
vulnerable to defects of mitochondrial oxidative
phosphorylation. Therefore, neurodegeneration is a hallmark
of mitochondrial diseases. The nervous system of affected
individuals typically shows selective regional vulnerability
leading to distinct patterns of tissue damage. A classic
example is Leigh syndrome, which causes symmetric
alterations of basal ganglia and brain stem. Leigh syndrome
can be caused by different genetic defects (>75 known
disease genes) with variable disease onset ranging from
infancy to adulthood. Other mitochondrial diseases are
characterized by focal brain lesions, which is a core
feature of MELAS syndrome (mitochondrial encephalopathy,
lactic acidosis, and stroke-like episodes). Apart from gray
matter, also white matter can be affected by mitochondrial
dysfunction. White matter lesions vary depending on the
underlying genetic defect and may progress into cystic
cavities. In view of the recognizable patterns of brain
damage in mitochondrial diseases, neuroimaging techniques
play a key role in diagnostic work-up. In the clinical
setting, magnetic resonance imaging (MRI) and MR
spectroscopy (MRS) are the mainstay of diagnostic work-up.
Apart from visualization of brain anatomy, MRS allows the
detection of metabolites such as lactate, which is of
specific interest in the context of mitochondrial
dysfunction. However, it is important to note that findings
like symmetric basal ganglia lesions on MRI or a lactate
peak on MRS are not specific, and that there is a broad
range of disorders that can mimic mitochondrial diseases on
neuroimaging. In this chapter, we will review the spectrum
of neuroimaging findings in mitochondrial diseases and
discuss important differential diagnoses. Moreover, we will
give an outlook on novel biomedical imaging tools that may
provide interesting insights into mitochondrial disease
pathophysiology.},
subtyp = {Review Article},
keywords = {Humans / Leigh Disease: diagnosis / Leigh Disease:
pathology / Magnetic Resonance Imaging: methods /
Neuroimaging: methods / Brain: pathology / Mitochondrial
Diseases: genetics / MELAS Syndrome: diagnosis / MELAS
Syndrome: pathology / Lactic Acid / Brain (Other) / Central
nervous system (Other) / Leigh disease (Other) / Magnetic
resonance imaging (Other) / Neurodegeneration (Other) /
OXPHOS (Other) / Lactic Acid (NLM Chemicals)},
cin = {Clinical Research (Munich)},
ddc = {610},
cid = {I:(DE-2719)1111015},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:36813312},
doi = {10.1016/b978-0-12-821751-1.00016-6},
url = {https://pub.dzne.de/record/255493},
}