TY - JOUR
AU - Schmitz, Anne S
AU - Korneck, Milena
AU - Raju, Janani
AU - Lamsfus-Calle, Andrés
AU - Daniel-Moreno, Alberto
AU - Antony, Justin S
AU - Mezger, Markus
AU - Schöls, Ludger
AU - Hauser, Stefan
AU - Hayer, Stefanie N
TI - Generation of a heterozygous and a homozygous CSF1R knockout line from iPSC using CRISPR/Cas9.
JO - Stem cell research
VL - 69
SN - 1873-5061
CY - Amsterdam [u.a.]
PB - Elsevier
M1 - DZNE-2023-00388
SP - 103066
PY - 2023
N1 - CC BY
AB - Mutations in Colony-stimulating factor 1 receptor (CSF1R) lead to CSF1R-related leukoencephalopathy, also known as Adult-onset leukoencephalopathy with axonal spheroids and pigmented glia (ALSP), a rapidly progressing neurodegenerative disease with severe cognitive and motor impairment. In this study, a homozygous and a heterozygous CSF1R knockout induced pluripotent stem cell (iPSC) line were generated by CRISPR/Cas9-based gene editing. These in vitro models will provide a helpful tool for investigating the still largely unknown pathophysiology of CSF1R-related leukoencephalopathy.
KW - Adult
KW - Humans
KW - Induced Pluripotent Stem Cells
KW - Neurodegenerative Diseases: genetics
KW - CRISPR-Cas Systems: genetics
KW - Neuroglia
KW - Leukoencephalopathies: genetics
KW - Mutation
LB - PUB:(DE-HGF)16
C6 - pmid:36947995
DO - DOI:10.1016/j.scr.2023.103066
UR - https://pub.dzne.de/record/257319
ER -