TY - JOUR
AU - Hipke, Katrin
AU - Pitter, Bettina
AU - Hruscha, Alexander
AU - van Bebber, Frauke
AU - Modic, Miha
AU - Bansal, Vikas
AU - Lewandowski, Sebastian A
AU - Orozco, Denise
AU - Edbauer, Dieter
AU - Bonn, Stefan
AU - Haass, Christian
AU - Pohl, Ulrich
AU - Montanez, Eloi
AU - Schmid, Bettina
TI - Loss of TDP-43 causes ectopic endothelial sprouting and migration defects through increased fibronectin, vcam 1 and integrin α4/β1.
JO - Frontiers in cell and developmental biology
VL - 11
SN - 2296-634X
CY - Lausanne
PB - Frontiers Media
M1 - DZNE-2023-00700
SP - 1169962
PY - 2023
AB - Aggregation of the Tar DNA-binding protein of 43 kDa (TDP-43) is a pathological hallmark of amyotrophic lateral sclerosis and frontotemporal dementia and likely contributes to disease by loss of nuclear function. Analysis of TDP-43 function in knockout zebrafish identified an endothelial directional migration and hypersprouting phenotype during development prior lethality. In human umbilical vein cells (HUVEC) the loss of TDP-43 leads to hyperbranching. We identified elevated expression of FIBRONECTIN 1 (FN1), the VASCULAR CELL ADHESION MOLECULE 1 (VCAM1), as well as their receptor INTEGRIN α4β1 (ITGA4B1) in HUVEC cells. Importantly, reducing the levels of ITGA4, FN1, and VCAM1 homologues in the TDP-43 loss-of-function zebrafish rescues the angiogenic defects indicating the conservation of human and zebrafish TDP-43 function during angiogenesis. Our study identifies a novel pathway regulated by TDP-43 important for angiogenesis during development.
KW - ALS (Other)
KW - TDP-43 (Other)
KW - angiogenesis (Other)
KW - neurodegeneration (Other)
KW - zebrafish (Other)
LB - PUB:(DE-HGF)16
C6 - pmid:37384248
C2 - pmc:PMC10299809
DO - DOI:10.3389/fcell.2023.1169962
UR - https://pub.dzne.de/record/258928
ER -