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@ARTICLE{Mynarek:272896,
author = {Mynarek, Martin and Rossius, Anne and Guiard, Anika and
Ottensmeier, Holger and von Hoff, Katja and Obrecht-Sturm,
Denise and Bußenius, Lisa and Friedrich, Carsten and von
Bueren, Andre O and Gerber, Nicolas U and Traunwieser,
Thomas and Kortmann, Rolf-Dieter and Warmuth-Metz, Monika
and Bison, Brigitte and Thomale, Ulrich-W and Krauss,
Juergen and Pietsch, Torsten and Clifford, Steven C and
Pfister, Stefan M and Sturm, Dominik and Sahm, Felix and
Tischler, Tanja and Rutkowski, Stefan},
title = {{R}isk factors for domain-specific neurocognitive outcome
in pediatric survivors of a brain tumor in the posterior
fossa-{R}esults of the {HIT} 2000 trial.},
journal = {Neuro-Oncology},
volume = {26},
number = {11},
issn = {1522-8517},
address = {Oxford},
publisher = {Oxford Univ. Press},
reportid = {DZNE-2024-01308},
pages = {2113 - 2124},
year = {2024},
abstract = {Neurocognition can be severely affected in pediatric brain
tumor survivors. We analyzed the association of cognitive
functioning with radiotherapy dose, postoperative cerebellar
mutism syndrome (pCMS), hydrocephalus, intraventricular
methotrexate (MTX) application, tumor localization, and
biology in pediatric survivors of a posterior fossa
tumor.Subdomain-specific neurocognitive outcome data from
279 relapse-free survivors of the HIT-2000 trial (241
medulloblastoma and 38 infratentorial ependymoma) using the
Neuropsychological Basic Diagnostic tool based on
Cattell-Horn-Carroll's model for intelligence were
analyzed.Cognitive performance 5.14 years (mean; range =
1.52-13.02) after diagnosis was significantly below normal
for all subtests. Processing speed and psychomotor abilities
were most affected. Influencing factors were
domain-specific: CSI-dose had a strong impact on most
subtests. pCMS was associated with psychomotor abilities (β
= -0.25 to -0.16) and processing speed (β = -0.32).
Postoperative hydrocephalus correlated with crystallized
intelligence (β = -0.20) and short-term memory (β =
-0.15), age with crystallized intelligence (β = 0.15) and
psychomotor abilities (β = -0.16 and β = -0.17). Scores
for fluid intelligence (β = -0.23), short-term memory (β =
-0.17) and visual processing (β = -0.25) declined, and
scores for selective attention improved (β = 0.29) with
time after diagnosis.The dose of CSI was strongly associated
with neurocognitive outcomes. Low psychomotor abilities and
processing speed both in patients treated with and without
CSI suggest a strong contribution of the tumor and its
surgery on these functions. Future research therefore should
analyze strategies to both reduce CSI dose and toxicity
caused by other treatment modalities.},
keywords = {Humans / Child / Female / Male / Infratentorial Neoplasms:
therapy / Adolescent / Child, Preschool / Medulloblastoma:
therapy / Risk Factors / Ependymoma: therapy /
Neuropsychological Tests / Cancer Survivors: psychology /
Cancer Survivors: statistics $\&$ numerical data / Follow-Up
Studies / Hydrocephalus: etiology / Cognition Disorders:
etiology / Prognosis / Mutism: etiology / ependymoma (Other)
/ infant (Other) / medulloblastoma (Other) /
neuropsychological late effects (Other) / quality of
survival (Other)},
cin = {Brainbank (Bonn)},
ddc = {610},
cid = {I:(DE-2719)1011009},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:38835160},
pmc = {pmc:PMC11534318},
doi = {10.1093/neuonc/noae092},
url = {https://pub.dzne.de/record/272896},
}