TY - JOUR
AU - Garrett, Lillian
AU - Trumbach, Dietrich
AU - Lee, Donghyung
AU - Mandillo, Silvia
AU - Samaco, Rodney
AU - Flenniken, Ann M.
AU - Stewart, Michelle
AU - Aguilar-Pimental, Juan A.
AU - Amarie, Oana V.
AU - Becker, Lore
AU - Calzada-Wack, Julia
AU - Da Silva-Buttkus, Patricia
AU - Dragano, Nathalia
AU - Kraiger, Markus
AU - Lengger, Christoph
AU - Leuchtenberger, Stefanie
AU - Marschall, Susan
AU - Oestereicher, Manuela A.
AU - Rathkolb, Birgit
AU - Sanz-Moreno, Adrián
AU - Seisenberger, Claudia
AU - Spielmann, Nadine
AU - Stoeger, Claudia
AU - Kumar, Vivek
AU - Keskivali, Piia
AU - King, Ruairidh
AU - Haselimashhadi, Hamed
AU - Bezginov, Alexandr
AU - Norris, Clare
AU - Taylor, Sarah
AU - Pimm, Dale
AU - Kelsey, Lois
AU - Berberovic, Zorana
AU - Qu, Dawei
AU - D'Souza, Abigail
AU - Bradaschia, Vivian
AU - Eskandarian, Mohammed
AU - Shang, Xueyuan
AU - Duffin, Kyle
AU - Roberton, Kyle
AU - Xu, Catherine
AU - Baguinat, Gloria
AU - Laurin, Valerie
AU - Lan, Qing
AU - Sleep, Gillian
AU - Lintott, Lauri
AU - Gertsenstein, Marina
AU - Tondat, Sandra
AU - Cruz, Maribelle
AU - Miller, David
AU - Bezginov, Alexandr
AU - Sorg, Tania
AU - Riet, Fabrice
AU - Tolentino, Heather
AU - Tolentino, Todd
AU - Schuchbauer, Mike
AU - Hockenbury, Nichole
AU - Beeman, Karrie
AU - Pedroia, Sheryl
AU - Salazar, Jason
AU - Heffner, Mollie
AU - Hsu, Joanne
AU - Fletcher, Colin
AU - Vanzanten, Maya
AU - Golini, Elisabetta
AU - Seavitt, John R.
AU - Lanza, Denise G.
AU - Lorenzo, Isabel
AU - Gaspero, Angelina
AU - Rios, Amanda
AU - White, Jacqueline K.
AU - McKerlie, Colin
AU - Nutter, Lauryl M. J.
AU - Vukobradovic, Igor
AU - Veeraragavan, Surabi
AU - Yuva, Lisa
AU - Heaney, Jason D.
AU - Dickinson, Mary E.
AU - Meziane, Hamid
AU - Hérault, Yann
AU - Wells, Sara
AU - Lloyd, K. C. Kent
AU - Bower, Lynette
AU - Lanoue, Louise
AU - Clary, Dave
AU - Zimprich, Annemarie
AU - Gailus-Durner, Valerie
AU - Fuchs, Helmut
AU - Brown, Steve D. M.
AU - Chesler, Elissa J.
AU - Wurst, Wolfgang
AU - Hrabě de Angelis, Martin
AU - Hölter, Sabine M.
TI - Co-expression of prepulse inhibition and Schizophrenia genes in the mouse and human brain
JO - Neuroscience Applied
VL - 3
SN - 2772-4085
CY - Amsterdam
PB - Elsevier
M1 - DZNE-2025-00094
SP - 104075
PY - 2024
AB - Schizophrenia is a complex psychiatric disorder with genetic and phenotypic heterogeneity. Accumulating rare and genome-wide association study (GWAS) common risk variant information has yet to yield robust mechanistic insight. Leveraging large-scale gene deletion mouse phenomic data thus has potential to functionally interrogate and prioritize human disease genes. To this end, we applied a cross-species network-based approach to parse an extensive mouse gene set (188 genes) associated with disrupted prepulse inhibition (PPI), a Schizophrenia endophenotype. Integrating PPI genes with high-resolution mouse and human brain transcriptomic data, we identified functional and disease coherent co-expression modules through hierarchical clustering and weighted gene co-expression network analysis (WGCNA). In two modules, Schizophrenia risk and mouse PPI genes converged based on telencephalic patterning. The associated neuronal genes were highly expressed in cingulate cortex and hippocampus; implicated in synaptic function and neurotransmission and overlapped with the greatest proportion of rare variants. Concordant neuroanatomical patterning revealed novel core Schizophrenia-relevant genes consistent with the Omnigenic hypothesis of complex traits. Among other genes discussed, the developmental and post-synaptic scaffold TANC2 (Tetratricopeptide repeat, ankyrin repeat and coiled-coil containing 2) emerged from both networks as a novel core genetic driver of Schizophrenia altering PPI. Aspects of psychiatric disease comorbidity and phenotypic heterogeneity are also explored. Overall, this study provides a framework and galvanizes the value of mouse preclinical genetics and PPI to prioritize both existing and novel human Schizophrenia candidate genes as druggable targets.
LB - PUB:(DE-HGF)16
DO - DOI:10.1016/j.nsa.2024.104075
UR - https://pub.dzne.de/record/275859
ER -