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@ARTICLE{Jrs:277796,
author = {Jürs, Alexandra V and Kasper, Elisabeth and Neumann,
Manuela and Kurth, Jens and Krause, Bernd J and Cantré,
Daniel and Prudlo, Johannes},
title = {{C}ase report: {B}ehavioral variant {FTD} confounding a
language variant {FTD} in a case of {PSP}-{CBS}.},
journal = {Frontiers in dementia},
volume = {4},
issn = {2813-3919},
address = {Lausanne, Switzerland},
publisher = {Frontiers Media S.A.},
reportid = {DZNE-2025-00474},
pages = {1540519},
year = {2025},
abstract = {Frontotemporal dementia (FTD) occurs in two main clinical
subtypes, which can transition into one another: the
behavioral variant (bvFTD) and the language variant (primary
progressive aphasia; PPA). It is common for the latter, as
primary progressive aphasia (PPA), to transition into bvFTD;
however, the opposite development, where bvFTD is followed
by 'secondary progressive aphasia,' has received little
attention. This constellation is particularly challenging to
recognize as frontal dysexecutive syndrome can confound
subsequent progressive aphasia as impulsive behavior, a lack
of inhibition, and apathy can lead to non-aphasic
communication disturbances, including impoverished syntax,
reduced cognitive flexibility, and insufficient error
monitoring. A 78-year-old patient, with a disease duration
of 10 years, was initially diagnosed in the 3rd year of the
disease with corticobasal syndrome (CBS) with frontal
behavioral-spatial syndrome (CBS-FBS) and subsequently with
CBS with progressive non-fluent aphasia (CBS-PNFA) in the
4th year. Severe ophthalmoplegia was the reason for changing
the diagnosis in the seventh year to progressive
supranuclear palsy with CBS predominance type (PSP-CBS). The
pathological diagnosis was FTLD-tau in the form of a PSP
subtype. The MRI showed asymmetric atrophy, particularly of
the left insular cortex and the left inferior frontal gyrus.
The 2-[18F]FDG-PET revealed left-accentuated bifrontal
glucose hypometabolism. This case report highlights how
progressive neurodegenerative aphasia can occur in FTD not
only as a primary language phenomenon (in the sense of PPA)
but also as a secondary phenomenon (following a primary
behavioral disorder with a non-aphasic communication
disorder). Dysexecutive syndrome can mask aphasia.
Therefore, incorporating spontaneous speech tasks into
standard neuropsychological language tests, in addition to
MRI and PET imaging techniques, could help better recognize
such secondary aphasias, even in the presence of
dysexecutive syndrome, and thus broaden our understanding of
the natural history of FTD.},
keywords = {behavioral variant (Other) / corticobasal syndrome (Other)
/ frontotemporal dementia (Other) / natural history (Other)
/ primary progressive aphasia (Other) / progressive
supranuclear palsy (Other)},
cin = {AG Teipel / AG Neumann},
ddc = {610},
cid = {I:(DE-2719)1510100 / I:(DE-2719)1210003},
pnm = {353 - Clinical and Health Care Research (POF4-353) / 352 -
Disease Mechanisms (POF4-352)},
pid = {G:(DE-HGF)POF4-353 / G:(DE-HGF)POF4-352},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:40144925},
pmc = {pmc:PMC11937099},
doi = {10.3389/frdem.2025.1540519},
url = {https://pub.dzne.de/record/277796},
}