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@ARTICLE{Ypez:281733,
author = {Yépez, Vicente A and Demidov, German and Ellwanger,
Kornelia and Laurie, Steven and Luknárová, Rebeka and
Joseph Maran, Midhuna Immaculate and Hentrich, Thomas and
Sagath, Lydia and van der Sanden, Bart and Astuti, Galuh and
Neveling, Kornelia and Batlle-Masó, Laura and Beijer,
Danique and Brechtmann, Felix and Caballero-Oteyza, Andrés
and Dabad, Marc and Denommé-Pichon, Anne-Sophie and
Doornbos, Cenna and Eddafir, Zakaria and Estévez-Arias,
Berta and Kilicarslan, Ozge Aksel and Kolen, Ingrid H M and
Kraß, Leon and Lohmann, Katja and Londhe, Shubhankar and
López-Martín, Estrella and Maassen, Kars and Macken,
William and Martínez-Delgado, Beatriz and Mei, Davide and
Mertes, Christian and Minardi, Raffaella and Morsy, Heba and
Mueller, Juliane S and Natera-de Benito, Daniel and Nelson,
Isabelle and Oud, Machteld M and Paramonov, Ida and Picó,
Daniel and Piscia, Davide and Polavarapu, Kiran and Raineri,
Emanuele and Savarese, Marco and Smal, Noor and Steehouwer,
Marloes and Steyaert, Wouter and Swertz, Morris A and
Thomsen, Mirja and Töpf, Ana and Van de Vondel, Liedewei
and van der Vries, Gerben and Vitobello, Antonio and Wilke,
Carlo and Zurek, Birte and T' Hoen, Peter-Bram and
Matalonga, Leslie and Vissers, Lisenka E L M and Gilissen,
Christian and Schulze-Hentrich, Julia and Beltran, Sergi and
Esteve-Codina, Anna and Hoischen, Alexander and Gagneur,
Julien and Graessner, Holm},
collaboration = {DITF-EPICARE, Solve-RD and DITF-ITHACA, Solve-RD and
DITF-EURO-NMD, Solve-RD and DITF-RITA, Solve-RD and
DITF-RND, Solve-RD and consortium, Solve-RD},
title = {{T}he {S}olve-{RD} {S}olvathons as a pan-{E}uropean
interdisciplinary collaboration to diagnose patients with
rare disease.},
journal = {Nature genetics},
volume = {57},
number = {10},
issn = {1061-4036},
address = {London},
publisher = {Macmillan Publishers Limited, part of Springer Nature},
reportid = {DZNE-2025-01166},
pages = {2361 - 2370},
year = {2025},
abstract = {Despite advances in genomic diagnostics, the majority of
individuals with rare diseases remain without a confirmed
genetic diagnosis. The rapid emergence of advanced omics
technologies, such as long-read genome sequencing, optical
genome mapping and multiomic profiling, has improved
diagnostic yield but also substantially increased analytical
and interpretational complexity. Addressing this complexity
requires systematic multidisciplinary collaboration, as
recently demonstrated by targeted diagnostic workshops.
Here, we highlight the experience of the Solve-RD
consortium, a pan-European initiative, in implementing four
structured workshops, termed 'Solvathons', as a regular and
effective component of its operational workflow. We provide
actionable insights, best practices and lessons learned for
successful data integration, expert training and scalable
collaborative diagnostics within large research consortia.},
keywords = {Rare Diseases: diagnosis / Rare Diseases: genetics / Humans
/ Europe / Genomics: methods / Genetic Testing: methods},
cin = {AG Gasser},
ddc = {570},
cid = {I:(DE-2719)1210000},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:40926087},
doi = {10.1038/s41588-025-02290-3},
url = {https://pub.dzne.de/record/281733},
}