TY - JOUR
AU - Verde, Federico
AU - Vávra, Jakub
AU - Dorst, J.
AU - Elmas, Zeynep
AU - Wiesenfarth, Maximilian
AU - De Gobbi, Anna
AU - Ratti, Antonia
AU - Poletti, Barbara
AU - Tumani, Hayrettin
AU - Weishaupt, Jochen
AU - Silani, Vincenzo
AU - Ticozzi, Nicola
AU - Otto, Markus
AU - Ludolph, Albert C
AU - Oeckl, Patrick
TI - CSF levels of the somatodendritic protein MAP2 are increased in ALS and predict shorter survival.
JO - Journal of neurology, neurosurgery, and psychiatry
VL - 96
IS - 12
SN - 0022-3050
CY - London
PB - BMJ Publishing Group
M1 - DZNE-2025-01265
SP - 1132 - 1143
PY - 2025
AB - Previous proteomic work has identified the somatodendritic protein MAP2 as a new candidate cerebrospinal fluid (CSF) biomarker for amyotrophic lateral sclerosis (ALS).We measured CSF levels of MAP2 and neurofilament light chain (NFL) in a retrospective cohort of 251 patients with ALS and 108 neurological controls (NCs).Patients with ALS had a higher median CSF MAP2 level compared with NCs, leading to an area under the curve (AUC) of 0.7080 (p<0.0001). They also had a higher median CSF NFL level (p<0.0001), resulting in an excellent diagnostic performance (AUC=0.9641; p<0.0001). Among patients with ALS, CSF MAP2 correlated with disease progression rate (DPR) (r=0.3099; p<0.0001) and was negatively associated with survival (HR=3.174). CSF NFL also correlated with DPR (r=0.4936; p<0.0001) and was negatively associated with survival (HR=2.759). The association of MAP2 with DPR was independent from NFL (p=0.0037). Stratifying patients based on median levels of both biomarkers resulted in significant differences in median survival times (low NFL/low MAP2, 66 months; high NFL/low MAP2 and vice versa, 35 months; high NFL/high MAP2, 26 months; p<0.0001). MAP2 was also associated with genetic status in patients with ALS, as patients with no mutations in C9ORF72 or in SOD1, as well as C9ORF72-positive ones, had higher median levels compared with NCs (p<0.0001), while patients with SOD1 mutations did not significantly differ from NCs (p>0.9999).Our study shows that the somatodendritic protein MAP2 is a promising candidate CSF biomarker for ALS.
KW - Humans
KW - Amyotrophic Lateral Sclerosis: cerebrospinal fluid
KW - Amyotrophic Lateral Sclerosis: mortality
KW - Amyotrophic Lateral Sclerosis: genetics
KW - Male
KW - Female
KW - Middle Aged
KW - Biomarkers: cerebrospinal fluid
KW - Neurofilament Proteins: cerebrospinal fluid
KW - Aged
KW - Retrospective Studies
KW - Microtubule-Associated Proteins: cerebrospinal fluid
KW - Disease Progression
KW - C9orf72 Protein: genetics
KW - Adult
KW - Superoxide Dismutase-1: genetics
KW - ALS (Other)
KW - CSF (Other)
KW - MOTOR NEURON DISEASE (Other)
KW - Biomarkers (NLM Chemicals)
KW - Neurofilament Proteins (NLM Chemicals)
KW - neurofilament protein L (NLM Chemicals)
KW - Microtubule-Associated Proteins (NLM Chemicals)
KW - MAP2 protein, human (NLM Chemicals)
KW - C9orf72 Protein (NLM Chemicals)
KW - Superoxide Dismutase-1 (NLM Chemicals)
KW - C9orf72 protein, human (NLM Chemicals)
LB - PUB:(DE-HGF)16
C6 - pmid:40537251
DO - DOI:10.1136/jnnp-2025-336208
UR - https://pub.dzne.de/record/282295
ER -