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@ARTICLE{Hu:282330,
author = {Hu, Jialu and Mantey, Richard and Guo, Hengyuan and Sidky,
Ahmed Mokhtar and Touhidinia, Maryam and Butt, Tanzeem and
Sobhani, Roohollah and Estrada, Santiago and Haendler,
Kristian and Zhao, Shixiao and Shang, Xuequn and De
Domenico, Elena and Beyer, Marc D. and Breteler, Monique M.
B. and Aziz, N. Ahmad},
title = {{G}enome-wide profiling of short tandem repeat somatic
instability reveals associations with age, sex and
brain-related traits},
reportid = {DZNE-2025-01291},
year = {2025},
abstract = {Short tandem repeats (STRs) are highly abundant in the
human genome and their age-related somatic instability is
emerging as a pivotal pathomechanism in repeat expansion
disorders. Nevertheless, currently no analysis tool exists
for genome-wide profiling of STR somatic instability. Here,
we present searchSTR, a novel computational framework that
enables accurate STR genotyping and somatic instability
quantification from both whole-genome and targeted
sequencing data. Applying this approach, we analyzed STR
variants from whole-genome sequencing data of the 1000
Genomes Project (n=3,202) and targeted deep-sequencing data
of the population-based Rhineland Study (n=2,974). We
provide a comprehensive multiancestry genome-wide reference
panel of STR variants and their somatic instability,
covering more than 1.4 million STRs across 26 populations.
Remarkably, STR somatic instability at many loci was
robustly associated with age, sex, brain morphology and
markers of neurodegeneration. These findings reveal a
crucial role for STR somatic instability as an age-dependent
modifier of brain structure.},
cin = {AG Aziz / AG Breteler / AG Beyer / AG Reuter / AG Schultze},
cid = {I:(DE-2719)5000071 / I:(DE-2719)1012001 /
I:(DE-2719)1013035 / I:(DE-2719)1040310 /
I:(DE-2719)1013038},
pnm = {354 - Disease Prevention and Healthy Aging (POF4-354) /
TRANSIT-ND - Tandem Repeats Associated with Neurogenomic
Somatic Instability and Neurodegeneration (101041677) / 351
- Brain Function (POF4-351)},
pid = {G:(DE-HGF)POF4-354 / G:(EU-Grant)101041677 /
G:(DE-HGF)POF4-351},
experiment = {EXP:(DE-2719)PRECISE-20190321},
typ = {PUB:(DE-HGF)25},
doi = {10.1101/2025.11.13.25340159},
url = {https://pub.dzne.de/record/282330},
}