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@INPROCEEDINGS{Wisch:283056,
author = {Wisch, Julie K and McKay, Nicole S and Zammit, Matthew D
and Christian, Bradley T and Schultz, Stephanie A and
Millar, Peter R and Barthélemy, Nicolas R and Ryan, Natalie
S and Renton, Alan E and Vermunt, Lisa and Joseph-Mathurin,
Nelly and Shirzadi, Zahra and Strain, Jeremy F and Chrem,
Patricio and Daniels, Alisha and Chhatwal, Jasmeer P and
Cruchaga, Carlos and Ibanez, Laura and Jucker, Mathias and
Day, Gregory S and Lee, Jae-Hong and Levin, Johannes and
Llibre-Guerra, Jorge J and Aguillon, David and Roh, Jee Hoon
and Supnet-Bell, Charlene and Xiong, Chengjie and Schindler,
Suzanne E and Wang, Guoqiao and Li, Yan and Koeppe, Robert
and Jack, Clifford R and Morris, John C and McDade, Eric and
Bateman, Randall J and Benzinger, Tammie L S and Ances, Beau
and Betthauser, Tobey J and Gordon, Brian A},
collaboration = {Network, Dominantly Inherited Alzheimer},
title = {{V}alidation of {A}myloid {C}hronicity in {A}utosomal
{D}ominant {A}lzheimer {D}isease},
journal = {Alzheimer's and dementia},
volume = {21},
number = {Suppl 2},
issn = {1552-5260},
reportid = {DZNE-2025-01463},
pages = {e103008},
year = {2025},
abstract = {Alzheimer Disease (AD) pathology evolves over decades, and
understanding this progression is critical to the
understanding of the disease and timing therapeutic
interventions. Since individuals with Autosomal Dominant AD
(ADAD) develop symptoms around the same age as their parent,
it is possible to predict symptom onset and stage
individuals by their estimated years to symptom onset (EYO).
This approach does not generalize to other forms of AD, thus
there is a pressing need for the timecourse of ADAD to be
defined in broadly relevant terms. The objective of this
project is to validate the Sampled Iterative Local
Approximation (SILA) algorithm in a cohort with a known
disease timecourse. SILA generates an estimate of time from
amyloid positivity (Atime) based on longitudinal PET data.We
evaluated Atime in a longitudinal ADAD sample (N = 316) with
PET PiB data in three ways. First, we compared predicted age
at amyloid positive (A+) to observed age at A+ for
individuals who became A+ during enrollment. Next, using
linear regression, we compared estimated age at A+ to
estimated age at symptom onset (EYO=0). Finally, we used
generalized additive models to compare the amount of
variance in concurrent cognitive performance explained both
Atime and EYO.We observed a mean average error of 1.15 years
between actual age at A+ (N = 26) and the SILA-predicted
Atime. Across all participants, SILA-estimated age at A+
explained $39\%$ of the variance in estimated age at symptom
onset (β = 0.918, p < 0.0001). Finally, we observed a
nonlinear association between cognition and both Atime and
EYO. Atime explained $19\%$ of the variance in the general
cognitive composite while EYO explained $43\%$ of the
variance.SILA produces a valid estimate of time-from-amyloid
positivity in ADAD. This work allows for disease stage in
ADAD to be compared to staging for broad forms of AD, which
was not previously possible using EYO. However, this work
also illustrates that there is a high degree of
heterogeneity in preclinical disease duration that is not
explained by amyloid alone.},
month = {Jul},
date = {2025-07-27},
organization = {Alzheimer’s Association
International Conference, Toronto
(Canada), 27 Jul 2025 - 31 Jul 2025},
keywords = {Humans / Alzheimer Disease: diagnostic imaging / Alzheimer
Disease: diagnosis / Alzheimer Disease: metabolism /
Positron-Emission Tomography / Male / Female / Biomarkers:
metabolism / Longitudinal Studies / Aged / Disease
Progression / Middle Aged / Algorithms / Amyloid
beta-Peptides: metabolism / Brain: diagnostic imaging /
Brain: metabolism / Biomarkers (NLM Chemicals) / Amyloid
beta-Peptides (NLM Chemicals)},
cin = {AG Jucker},
ddc = {610},
cid = {I:(DE-2719)1210001},
pnm = {352 - Disease Mechanisms (POF4-352)},
pid = {G:(DE-HGF)POF4-352},
typ = {PUB:(DE-HGF)1 / PUB:(DE-HGF)16},
pubmed = {pmid:41451762},
pmc = {pmc:PMC12741810},
doi = {10.1002/alz70856_103008},
url = {https://pub.dzne.de/record/283056},
}