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@INPROCEEDINGS{Tsvetanov:283069,
author = {Tsvetanov, Kamen A and Jones, P Simon and Malpetti, Maura
and Rittman, Timothy and Bouzigues, Arabella and van
Swieten, John and Jiskoot, Lize and Seelaar, Harro and
Borroni, Barbara and Premi, Enrico and Sanchez-Valle, Raquel
and Moreno, Fermin and Laforce, Robert and Graff, Caroline
and Synofzik, Matthis and Galimberti, Daniela and Masellis,
Mario and Tartaglia, Carmela and Finger, Elizabeth and
Vandenberghe, Rik and de Mendonça, Alexandre and
Tagliavini, Fabrizio and Santana, Isabel and Ducharme, Simon
and Butler, Christopher and Gerhard, Alexander and Levin,
Johannes and Otto, Markus and Sorbi, Sandro and Russell,
Lucy L and Rohrer, Jonathan D and Rowe, James B},
collaboration = {Genetic FTD Initiative, GENFI},
title = {{S}tructure‐function decoupling in genetic frontotemporal
dementia},
journal = {Alzheimer's and dementia},
volume = {21},
number = {Suppl 2},
issn = {1552-5260},
reportid = {DZNE-2025-01476},
pages = {e100438},
year = {2025},
abstract = {Functional network integrity is important for maintaining
cognitive performance during the 10-20 year presymptomatic
period of frontotemporal dementia (FTD), conferring
resilience to advancing neuropathology and atrophy. The
extent to which functional integrity relies on preserved
structural connectivity is unclear. Here, we test the
relationship between functional connectivity and structural
connectivity, termed structure-function coupling, against
genetic risk for FTD and disease progression.We studied 56
symptomatic and 165 pre-symptomatic FTD-mutation carriers,
and 141 family members without mutations, from the GENFI
cohort. Diffusion weighted imaging and functional magnetic
resonance imaging (Siemens MR platforms) were acquired and
analysed using established approaches to quantify
participant-level structural and functional connectomes
(Figure 1-(1)). Connectomes were defined in the Brainnetome
Atlas and re-mapped onto a subcortical network and seven
resting-state networks based on the Yeo Networks (Figure
1-(2)). An inter-subject regularized canonical correlation
analysis (CCA) with permutation-based cross-validation was
used to jointly analyse the structural and functional
connectomes (Figure 1-(3-4)). Second-level analysis with
robust multiple linear regression models tested for
differences between non-carriers, pre-symptomatic carriers
and symptomatic carriers in the strength of association
between structural and functional CCA subject scores. Age,
sex, head motion and scanner site were included as
covariates.Canonical correlation analysis identified
significant components linking structural and functional
connectivity. The first component (r=0.656, p <0.001)
reflected a structural connectivity pattern with high
within- and between-networks loadings (Figure 1-(5)) with
strong within-networks functional connectivity and
weak-to-negative between-network functional connectivity
(Figure 1-(6)). This component associated structural
integrity with function segregation, whereby individuals
with high structural connectivity within and between
networks exhibit greater functional network segregation as
shown by strong within-network functional connectivity and
weak between network connectivity. The strength of this
structure-function coupling was greater for non-carriers
compared to pre-symptomatic carriers (Figure 1-(7)).
Symptomatic carriers showed minimal relationship between
structural and functional scores, indicating
structure-function decoupling, consistent with the
hypothesis that cognitive decline is triggered by critical
decoupling of previously synergistic neural systems.Our
findings demonstrate progressive de-coupling between
structural connectivity and functional segregation over the
course of genetic frontotemporal dementia. These results
have implications for designing pre-symptomatic
disease-modifying 'preventative' trials, supported by
imaging-based surrogate markers of neural system dynamics.},
month = {Jul},
date = {2025-07-27},
organization = {Alzheimer’s Association
International Conference, Toronto
(Canada), 27 Jul 2025 - 31 Jul 2025},
keywords = {Humans / Male / Female / Frontotemporal Dementia: genetics
/ Frontotemporal Dementia: diagnostic imaging /
Frontotemporal Dementia: physiopathology / Frontotemporal
Dementia: pathology / Middle Aged / Magnetic Resonance
Imaging / Connectome / Biomarkers / Brain: physiopathology /
Brain: diagnostic imaging / Brain: pathology / Aged /
Disease Progression / Mutation: genetics / Adult / Cohort
Studies / Neural Pathways: physiopathology / Neural
Pathways: diagnostic imaging / Diffusion Magnetic Resonance
Imaging / Biomarkers (NLM Chemicals)},
cin = {AG Gasser / Clinical Research (Munich) / AG Levin},
ddc = {610},
cid = {I:(DE-2719)1210000 / I:(DE-2719)1111015 /
I:(DE-2719)1111016},
pnm = {353 - Clinical and Health Care Research (POF4-353)},
pid = {G:(DE-HGF)POF4-353},
typ = {PUB:(DE-HGF)1 / PUB:(DE-HGF)16},
pubmed = {pmid:41447690},
pmc = {pmc:PMC12740290},
doi = {10.1002/alz70856_100438},
url = {https://pub.dzne.de/record/283069},
}