TY - JOUR
AU - Lange, Lara M
AU - Fang, Zih-Hua
AU - Screven, Laurel
AU - Tan, Ai Huey
AU - Alcalay, Roy N
AU - Amouri, Rim
AU - Bovenzi, Roberta
AU - Fenn, Matilda
AU - Frost, Joshua L I
AU - Jankovic, Joseph
AU - Jasaityte, Simona
AU - Jaunmuktane, Zane
AU - Jeon, Beomseok
AU - Sarmiento, Ignacio Juan Keller
AU - Krüger, Rejko
AU - Kuhlenbäumer, Gregor
AU - Lin, Chin-Hsien
AU - Pavelka, Lukas
AU - Periñan, Maria Teresa
AU - Sassi, Samia Ben
AU - Schirinzi, Tommaso
AU - Shin, Jung Hwan
AU - Shulman, Joshua M
AU - Tay, Yi Wen
AU - Uitti, Ryan
AU - Warner, Tom
AU - Wszolek, Zbigniew K
AU - Wu, Lesley
AU - Wu, Ruey-Meei
AU - Zeuner, Kirsten E
AU - Blauwendraat, Cornelis
AU - Singleton, Andrew
AU - Mencacci, Niccolò E
AU - Morris, Huw R
AU - Lim, Shen-Yang
AU - Lohmann, Katja
AU - Klein, Christine
TI - Rare but Relevant? Assessing Variants in Dystonia-Linked Genes in Parkinson's Disease.
JO - Movement disorders
VL - 41
IS - 1
SN - 0885-3185
CY - New York, NY
PB - Wiley
M1 - DZNE-2026-00169
SP - 247 - 259
PY - 2026
AB - Dystonia and Parkinson's disease (PD) exhibit clinical and genetic overlap, but the relevance of dystonia gene variants in PD remains unclear.The aim was to assess the frequency of dystonia-linked pathogenic variants in PD.We screened sequencing data from 15,684 individuals (8272 PD, 3200 atypical parkinsonism, and 4212 unaffected) from the Global Parkinson's Genetics Program (GP2) and Accelerating Medicines Partnership-Parkinson's Disease (AMP-PD) for variants in genes linked to isolated dystonia, dystonia-parkinsonism, and myoclonus-dystonia.Pathogenic variants were identified only in PD patients. Forty-five PD individuals (0.54
KW - Humans
KW - Parkinson Disease: genetics
KW - Parkinson Disease: complications
KW - Male
KW - Female
KW - Middle Aged
KW - Dystonia: genetics
KW - Aged
KW - GTP Cyclohydrolase: genetics
KW - Dystonic Disorders: genetics
KW - Adult
KW - Vesicular Transport Proteins: genetics
KW - GCH1 (Other)
KW - Parkinson's disease (Other)
KW - VPS16 (Other)
KW - dystonia (Other)
KW - monogenic (Other)
KW - GTP Cyclohydrolase (NLM Chemicals)
KW - GCH1 protein, human (NLM Chemicals)
KW - Vesicular Transport Proteins (NLM Chemicals)
LB - PUB:(DE-HGF)16
C6 - pmid:41074695
C2 - pmc:PMC12882037
DO - DOI:10.1002/mds.70073
UR - https://pub.dzne.de/record/285045
ER -