TY - JOUR
AU - Vogel, Adam P
AU - Graf, Lisa
AU - Weiß, Merit
AU - Chan, Cheuk S J
AU - Hepworth, Graham
AU - Synofzik, Matthis
TI - Development and validation of the dysarthria impact scale: a patient-reported outcome for motor speech disorders.
JO - Journal of neurology
VL - 273
IS - 3
SN - 0367-004X
CY - [Darmstadt]
PB - Steinkopff
M1 - DZNE-2026-00273
SP - 195
PY - 2026
AB - Impaired speech due to dysarthria significantly impacts quality of life. Patient-reported outcomes (PROs) offer critical insight into the lived experience of communication disability and are central to regulatory frameworks for patient-focused drug development.To develop and validate the Dysarthria Impact Scale (DIS), a brief PRO designed to assess the impact of motor speech disorders on quality of life across neurological conditions.A multi-site, cross-sectional study was conducted with 244 participants, including individuals with Huntington's disease, Parkinson's disease, hereditary ataxias, and head and neck cancer, and healthy controls. The 22-item DIS was developed using expert input and patient feedback and evaluated alongside reference tools (Voice Handicap Index and SF-36). Item reduction procedures yielded two shorter versions (DIS-17 and DIS-6). Validity, reliability, and sensitivity/specificity analyses were performed, and minimal clinically important differences (MCIDs) were estimated using distribution-based methods.All DIS versions showed strong convergent validity with the VHI (r = -0.85) and SF-36 (r = 0.72) and were correlated with blinded perceptual speech ratings. DIS-17 and DIS-6 achieved comparable sensitivity (0.93 and 0.88) and specificity (0.84 and 0.86, respectively). Test-retest reliability was high (r = 0.98), with estimated MCIDs and within-subject variability provided. Group differences were observed, with lower DIS scores in ataxia and Parkinson's disease compared to Huntington's disease.The DIS is a valid, reliable, and practical PRO for quantifying the impact of dysarthria on quality of life. Longitudinal responsiveness remains to be established.
KW - Humans
KW - Dysarthria: diagnosis
KW - Dysarthria: etiology
KW - Dysarthria: psychology
KW - Male
KW - Female
KW - Middle Aged
KW - Patient Reported Outcome Measures
KW - Aged
KW - Cross-Sectional Studies
KW - Adult
KW - Reproducibility of Results
KW - Quality of Life
KW - Severity of Illness Index
KW - Clinical trials (Other)
KW - Dysarthria (Other)
KW - Patient-reported outcome (Other)
KW - Questionnaire (Other)
KW - Speech (Other)
KW - Survey (Other)
LB - PUB:(DE-HGF)16
C6 - pmid:41805906
C2 - pmc:PMC12975812
DO - DOI:10.1007/s00415-026-13740-1
UR - https://pub.dzne.de/record/285634
ER -